Nonpeptide orexin type-2 receptor agonist ameliorates narcolepsy-cataplexy symptoms in mouse models.

نویسندگان

  • Yoko Irukayama-Tomobe
  • Yasuhiro Ogawa
  • Hiromu Tominaga
  • Yukiko Ishikawa
  • Naoto Hosokawa
  • Shinobu Ambai
  • Yuki Kawabe
  • Shuntaro Uchida
  • Ryo Nakajima
  • Tsuyoshi Saitoh
  • Takeshi Kanda
  • Kaspar Vogt
  • Takeshi Sakurai
  • Hiroshi Nagase
  • Masashi Yanagisawa
چکیده

Narcolepsy-cataplexy is a debilitating disorder of sleep/wakefulness caused by a loss of orexin-producing neurons in the lateroposterior hypothalamus. Genetic or pharmacologic orexin replacement ameliorates symptoms in mouse models of narcolepsy-cataplexy. We have recently discovered a potent, nonpeptide OX2R-selective agonist, YNT-185. This study validates the pharmacological activity of this compound in OX2R-transfected cells and in OX2R-expressing neurons in brain slice preparations. Intraperitoneal, and intracerebroventricular, administration of YNT-185 suppressed cataplexy-like episodes in orexin knockout and orexin neuron-ablated mice, but not in orexin receptor-deficient mice. Peripherally administered YNT-185 also promotes wakefulness without affecting body temperature in wild-type mice. Further, there was no immediate rebound sleep after YNT-185 administration in active phase in wild-type and orexin-deficient mice. No desensitization was observed after repeated administration of YNT-185 with respect to the suppression of cataplexy-like episodes. These results provide a proof-of-concept for a mechanistic therapy of narcolepsy-cataplexy by OX2R agonists.

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عنوان ژورنال:
  • Proceedings of the National Academy of Sciences of the United States of America

دوره 114 22  شماره 

صفحات  -

تاریخ انتشار 2017